Introduction:
Biliary cystadenoma is an extremely rare clinical entity, even more so when located in the extrahepatic biliary tree in comparison to their intrahepatic counterparts [1]. It accounts for less than 5% of all cystic lesions of liver [2]. Less than 50 cases are reported in existing medical literature. It is typically seen in middle aged female and thought to have hormonal factors like estrogen and progesterone responsible for its pathogenesis [3]. Many a times, it is hard to diagnose due to its vague clinical signs and symptoms, prolonged clinical course and difficult radiological interpretations. Although there are no cases of extrahepatic biliary cystadenomas presenting with gastric outlet obstruction and ours is the first of its kind. The case report was realized according to international Surgical CAse REport (SCARE) guidelines [4].